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            <r:String xml:lang="sv">Excessive premature mortality among children with cerebral palsy in rural Uganda: a longitudinal, population-based study</r:String>
            <r:String xml:lang="en">Excessive premature mortality among children with cerebral palsy in rural Uganda: a longitudinal, population-based study</r:String>
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            <a:FirstGiven>Angelina</a:FirstGiven>
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              <r:String>Angelina Kakooza-Mwesige</r:String>
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      <r:Title>
        <r:String xml:lang="sv">Functional development in children and youth with cerebral palsy in Uganda</r:String>
        <r:String xml:lang="en">Functional development in children and youth with cerebral palsy in Uganda</r:String>
      </r:Title>
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      <r:Publisher>
        <r:PublisherName>
          <r:String xml:lang="sv">Karolinska Institutet</r:String>
          <r:String xml:lang="en">Karolinska Institutet</r:String>
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      <r:Publisher>
        <r:PublisherName>
          <r:String xml:lang="sv">Karolinska Institutet</r:String>
          <r:String xml:lang="en">Karolinska Institutet</r:String>
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      <r:PublicationDate>
        <r:SimpleDate>2021-08-19</r:SimpleDate>
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        <r:IdentifierContent>10.5878/txww-hg72</r:IdentifierContent>
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      <r:Content xml:lang="sv">Syfte 
Att följa den funktionella utvecklingen för en populationsbaserad kohort av barn och ungdomar med cerebral pares (CP) på landsbygden i Uganda, och jämföra deras utveckling med utvecklingskurvor från höginkomstländer. 

Metod 
81 barn och ungdomar mellan 2-17 år undersöktes 2015 och 2019 med Gross Motor Function Measure-66 (GMFM-66) Pediatric Evaluation of Disability Inventory, Ugandan version (PEDI-UG), och funktionella klassifikationssystem.

Datasetet består av följande filer:
- Functional_development_in Uganda_dataset_Andrews_et_al.csv
- Variable_list_for_functional_development_in_Uganda_dataset_Andrews_et_al.pdf

Information om verktyget Gross Motor Function Measure-66 (GMFM-66):
https://www.canchild.ca/en/resources/44-gross-motor-function-measure-gmfm</r:Content>
      <r:Content xml:lang="en">AIM
To follow the functional development of a population-based cohort of children and youth (C&amp;Y) with cerebral palsy (CP) in rural Uganda and compare their development with developmental trajectories from high-income countries (HIC). 
 
METHODS
Eighty-one C&amp;Y aged 2–17 years with CP were assessed 2015 and 2019 using Gross Motor Function Measure-66 items (GMFM-66), Pediatric Evaluation of Disability Inventory, Ugandan version (PEDI-UG), and functional classification systems. We calculated scaled scores (actual scores) and reference scores (amount of deviation from HIC developmental trajectories). Wilcoxon signed rank test was used for statistical analyses. 

RESULTS
C&amp;Y with CP in Uganda exhibited no differences in scaled scores between the first and second assessments for GMFM-66 and PEDI-UG mobility skills, while they exhibited increased PEDI-UG self-care skills (p&lt;0.001). Reference scores were more negative at the second assessment than at the first assessment for GMFM-66 (p=0.002) and PEDI-UG mobility (p=0.036) but not for PEDI-UG self-care. The increased difference in reference scores over the 4 years were primarily driven by younger children (2–5 years) and C&amp;Y with milder impairments. 

INTERPRETATION
The increased difference in reference scores between assessments suggests that C&amp;Y with CP in Uganda develop motor skills at a lower rate than peers in HIC.

The dataset contains of the following files:
- Functional_development_in Uganda_dataset_Andrews_et_al.csv
- Variable_list_for_functional_development_in_Uganda_dataset_Andrews_et_al.pdf

Information about the tool Gross Motor Function Measure-66 (GMFM-66):
https://www.canchild.ca/en/resources/44-gross-motor-function-measure-gmfm</r:Content>
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